caa a22 4500 445374489 CHVBK 20180317142958.0 cr unu---uuuuu 170323e20110401xx s 000 0 eng 10.1007/s00540-010-1080-5 doi (NATIONALLICENCE)springer-10.1007/s00540-010-1080-5 A novel association of alveolar capillary dysplasia, atypical duodenal atresia, and subglottic stenosis [Elektronische Daten] [Takeru Shimizu, Taeko Fukuda, Shinichi Inomata, Tsuyoshi Satsumae, Makoto Tanaka] Alveolar capillary dysplasia (ACD), which is a rare and lethal congenital pulmonary anomaly found in newborns, begins its onset or causes deterioration of the infant's condition some time after birth. Various congenital anomalies in combination with ACD have been reported, except for subglottic stenosis. Therefore, we aim to report a novel association in a case of ACD with the combination of atypical duodenal atresia and subglottic stenosis. The male infant was scheduled for duodeno-duodenostomy because a double-bubble sign was observed on a chest radiograph. He arrived at the operating theater without any symptoms. After induction of general anesthesia, although mask ventilation was performed without difficulties throughout the entire procedure, oxygen saturation values of the upper and lower extremities dissociated after several attempts of intubation. Surgery was canceled because of instability of the respiratory condition. Respiratory insufficiency worsened progressively, and the infant died at 5days of age. An autopsy confirmed ACD and revealed cartilaginous subglottic stenosis, which had made intubation difficult. This report highlights the hazards of the onset and worsening of ACD, and the importance of thorough echocardiography before surgery when atypical duodenal atresia is suspected. Anesthesiologists should also be prepared for the difficulty of intubation. Japanese Society of Anesthesiologists, 2010 Alveolar capillary dysplasia nationallicence Atypical duodenal atresia nationallicence Subglottic stenosis nationallicence Shimizu Takeru Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut Fukuda Taeko Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut Inomata Shinichi Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut Satsumae Tsuyoshi Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut Tanaka Makoto Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut Journal of Anesthesia Springer Japan 25/2(2011-04-01), 298-300 0913-8668 25:2<298 2011 25 540 https://doi.org/10.1007/s00540-010-1080-5 text/html Onlinezugriff via DOI 1 research-article jats NATIONALLICENCE 856 40 https://doi.org/10.1007/s00540-010-1080-5 text/html Onlinezugriff via DOI NATIONALLICENCE 700 1- Shimizu Takeru Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut NATIONALLICENCE 700 1- Fukuda Taeko Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut NATIONALLICENCE 700 1- Inomata Shinichi Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut NATIONALLICENCE 700 1- Satsumae Tsuyoshi Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut NATIONALLICENCE 700 1- Tanaka Makoto Department of Anesthesiology and Critical Care Medicine, Graduate School of Comprehensive Human Sciences, University of Tsukuba, 1-1-1 Tennodai, 305-8575, Tsukuba, Ibaraki, Japan aut NATIONALLICENCE 773 0- Journal of Anesthesia Springer Japan 25/2(2011-04-01), 298-300 0913-8668 25:2<298 2011 25 540 Metadata rights reserved Springer special CC-BY-NC licence nationallicence BK010053 XK010053 XK010000 NATIONALLICENCE NATIONALLICENCE NL-springer