caa a22 4500 606179755 CHVBK 20210128100802.0 cr unu---uuuuu 210128e20150401xx s 000 0 eng 10.1007/s11136-014-0826-1 doi (NATIONALLICENCE)springer-10.1007/s11136-014-0826-1 Living with orofacial conditions: psychological distress and quality of life in adults affected with Treacher Collins syndrome, cherubism, or oligodontia/ectodermal dysplasia—a comparative study [Elektronische Daten] [Amy Geirdal, Solfrid Saltnes, Kari Storhaug, Pamela Åsten, Hilde Nordgarden, Janicke Jensen] Purpose: The relationship between quality of life, psychological distress, and orofacial syndromes in children and adolescents has been reported in several studies. However, little is known about differences in psychological distress and quality of life among adults with different orofacial conditions. Therefore, the aims of this study were to examine and compare these factors among three groups of adults affected by Treacher Collins syndrome (TCS), cherubism, and oligodontia/ectodermal dysplasia (ED). Methods: We included 11 individuals with TCS (mean age 46.9, SD 12.9years), 15 with cherubism (mean age 50.3, SD 16.8years), and 49 with oligodontia/ED (mean age 30.7, SD 15.6years). The respondents completed questionnaires related to psychological distress and quality of life. Results: The oligodontia/ED group had a significantly higher level of anxiety and worse mental health-related quality of life than both the TCS and cherubism groups. Adults with TCS reported the highest level of depression, and the lowest levels of overall quality of life, well-being, and physical health-related quality of life. The cherubism group displayed the best overall quality of life, well-being, and mental health. Conclusions: Psychological distress and quality of life differed in various orofacial conditions. This study provided insight into these aspects that may contribute to improved care. The Author(s), 2014 Psychological distress nationallicence Quality of life nationallicence Treacher Collins syndrome nationallicence Cherubism nationallicence Oligodontia/ectodermal dysplasia nationallicence Geirdal Amy Faculty of Social Sciences, Oslo and Akershus University College of Applied Sciences, Oslo, Norway aut Saltnes Solfrid TAKO-Centre, Lovisenberg Diakonale Hospital, Oslo, Norway aut Storhaug Kari TAKO-Centre, Lovisenberg Diakonale Hospital, Oslo, Norway aut Åsten Pamela TAKO-Centre, Lovisenberg Diakonale Hospital, Oslo, Norway aut Nordgarden Hilde TAKO-Centre, Lovisenberg Diakonale Hospital, Oslo, Norway aut Jensen Janicke Department of Oral Surgery and Oral Medicine, Faculty of Dentistry, University of Oslo, Oslo, Norway aut Quality of Life Research Springer International Publishing 24/4(2015-04-01), 927-935 0962-9343 24:4<927 2015 24 11136 https://doi.org/10.1007/s11136-014-0826-1 text/html Onlinezugriff via DOI BK010053 XK010053 XK010000 Metadata rights reserved Springer special CC-BY-NC licence nationallicence 1 research-article jats NATIONALLICENCE NATIONALLICENCE NL-springer NATIONALLICENCE 856 40 https://doi.org/10.1007/s11136-014-0826-1 text/html Onlinezugriff via DOI NATIONALLICENCE 700 1- Geirdal Amy Faculty of Social Sciences, Oslo and Akershus University College of Applied Sciences, Oslo, Norway aut NATIONALLICENCE 700 1- Saltnes Solfrid TAKO-Centre, Lovisenberg Diakonale Hospital, Oslo, Norway aut NATIONALLICENCE 700 1- Storhaug Kari TAKO-Centre, Lovisenberg Diakonale Hospital, Oslo, Norway aut NATIONALLICENCE 700 1- Åsten Pamela TAKO-Centre, Lovisenberg Diakonale Hospital, Oslo, Norway aut NATIONALLICENCE 700 1- Nordgarden Hilde TAKO-Centre, Lovisenberg Diakonale Hospital, Oslo, Norway aut NATIONALLICENCE 700 1- Jensen Janicke Department of Oral Surgery and Oral Medicine, Faculty of Dentistry, University of Oslo, Oslo, Norway aut NATIONALLICENCE 773 0- Quality of Life Research Springer International Publishing 24/4(2015-04-01), 927-935 0962-9343 24:4<927 2015 24 11136